Spinal epidural Rosai-Dorfman disease preceding by relapsing uveitis: A case report with literature review

Y. C. Huang; H. Y. Tan; S. M. Jung; W. Y. Chuang; C. C. Chuang; P. W. Hsu; Chen-Nen Chang

doi:10.1038/sj.sc.3102006

Spinal epidural Rosai-Dorfman disease preceding by relapsing uveitis: A case report with literature review

Y. C. Huang, H. Y. Tan, S. M. Jung, W. Y. Chuang, C. C. Chuang, P. W. Hsu, Chen-Nen Chang^*

^*Corresponding author for this work

School of Medicine

Research output: Contribution to journal › Journal Article › peer-review

16 Scopus citations

Abstract

Study design: Case report. Setting: Tertiary referral center hospital in Taiwan. Objectives: To report a case of spinal Rosai-Dorfman disease (RDD) presenting with paraparesis and also preceding by relapsing uveitis for 6 months. A thoracic laminectomy was performed to remove the solid mass. The pathological diagnosis reveals infiltrating histiocytes, emperipolesis and positivity for S-100. There is no recurrence 1 year later with MR imaging. Conclusions: The relapsing idiopathic uveitis may be a prodrome for this unusual disease, because RDD is associated closely to defective immunogical response. Early and accurate diagnosis of CNS RDD may reverse the neurologic deficits by early decompression.

Original language	English
Pages (from-to)	641-644
Number of pages	4
Journal	Spinal Cord
Volume	45
Issue number	9
DOIs	https://doi.org/10.1038/sj.sc.3102006
State	Published - 07 09 2007

Keywords

Rosai-Dorfman disease
Sinus histiocytosis
Spinal neoplasm
Uveitis

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title = "Spinal epidural Rosai-Dorfman disease preceding by relapsing uveitis: A case report with literature review",

abstract = "Study design: Case report. Setting: Tertiary referral center hospital in Taiwan. Objectives: To report a case of spinal Rosai-Dorfman disease (RDD) presenting with paraparesis and also preceding by relapsing uveitis for 6 months. A thoracic laminectomy was performed to remove the solid mass. The pathological diagnosis reveals infiltrating histiocytes, emperipolesis and positivity for S-100. There is no recurrence 1 year later with MR imaging. Conclusions: The relapsing idiopathic uveitis may be a prodrome for this unusual disease, because RDD is associated closely to defective immunogical response. Early and accurate diagnosis of CNS RDD may reverse the neurologic deficits by early decompression.",

keywords = "Rosai-Dorfman disease, Sinus histiocytosis, Spinal neoplasm, Uveitis",

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doi = "10.1038/sj.sc.3102006",

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T2 - A case report with literature review

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AU - Jung, S. M.

AU - Chuang, W. Y.

AU - Chuang, C. C.

AU - Hsu, P. W.

AU - Chang, Chen-Nen

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N2 - Study design: Case report. Setting: Tertiary referral center hospital in Taiwan. Objectives: To report a case of spinal Rosai-Dorfman disease (RDD) presenting with paraparesis and also preceding by relapsing uveitis for 6 months. A thoracic laminectomy was performed to remove the solid mass. The pathological diagnosis reveals infiltrating histiocytes, emperipolesis and positivity for S-100. There is no recurrence 1 year later with MR imaging. Conclusions: The relapsing idiopathic uveitis may be a prodrome for this unusual disease, because RDD is associated closely to defective immunogical response. Early and accurate diagnosis of CNS RDD may reverse the neurologic deficits by early decompression.

AB - Study design: Case report. Setting: Tertiary referral center hospital in Taiwan. Objectives: To report a case of spinal Rosai-Dorfman disease (RDD) presenting with paraparesis and also preceding by relapsing uveitis for 6 months. A thoracic laminectomy was performed to remove the solid mass. The pathological diagnosis reveals infiltrating histiocytes, emperipolesis and positivity for S-100. There is no recurrence 1 year later with MR imaging. Conclusions: The relapsing idiopathic uveitis may be a prodrome for this unusual disease, because RDD is associated closely to defective immunogical response. Early and accurate diagnosis of CNS RDD may reverse the neurologic deficits by early decompression.

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Spinal epidural Rosai-Dorfman disease preceding by relapsing uveitis: A case report with literature review

Abstract

Keywords

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